Drosophila Bld10 Is a Centriolar Protein That Regulates Centriole, Basal Body, and Motile Cilium Assembly

V Mottier-Pavie, TL Megraw - Molecular biology of the cell, 2009 - Am Soc Cell Biol
V Mottier-Pavie, TL Megraw
Molecular biology of the cell, 2009Am Soc Cell Biol
Cilia and flagella play multiple essential roles in animal development and cell physiology.
Defective cilium assembly or motility represents the etiological basis for a growing number of
human diseases. Therefore, how cilia and flagella assemble and the processes that drive
motility are essential for understanding these diseases. Here we show that Drosophila
Bld10, the ortholog of Chlamydomonas reinhardtii Bld10p and human Cep135, is a
ubiquitous centriolar protein that also localizes to the spermatid basal body. Mutants that …
Cilia and flagella play multiple essential roles in animal development and cell physiology. Defective cilium assembly or motility represents the etiological basis for a growing number of human diseases. Therefore, how cilia and flagella assemble and the processes that drive motility are essential for understanding these diseases. Here we show that Drosophila Bld10, the ortholog of Chlamydomonas reinhardtii Bld10p and human Cep135, is a ubiquitous centriolar protein that also localizes to the spermatid basal body. Mutants that lack Bld10 assemble centrioles and form functional centrosomes, but centrioles and spermatid basal bodies are short in length. bld10 mutant flies are viable but male sterile, producing immotile sperm whose axonemes are deficient in the central pair of microtubules. These results show that Drosophila Bld10 is required for centriole and axoneme assembly to confer cilium motility.
Am Soc Cell Biol